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S!$ᴭAEt+& E'c9abv @z .zyӝNfCU7f胕zr*+J`H>d "gӱ @ė-,:kS|gjxhW$f;]j[ endstream endobj 25 0 obj <>stream hތn@qz#\böTZ*H$-a)M*DOF9ܸs[ n9ech=ϳ;}RV0+ YFL,R!*`eX(:SM yԄ8򡫰|?b%4B@BCNh? ^^ևA nE>z1>?NQOIRƚYQ"&b'Y}sӫ_[$ƭɛy5ܙcv'Wm}y} \n>stream 2025-03-14T14:14:30+08:00 2025-03-14T14:14:28+08:00 2025-03-14T14:14:30+08:00 Acrobat PDFMaker 11 Word 版 uuid:777adc1a-7eb5-4bb5-b69e-9fb8bc8ee813 uuid:a895d009-0e27-41c2-bff0-b1c615a8bb07 63 application/pdf 儿童威廉姆斯综合征1例及文献复习 目的:报告1例威廉姆斯综合征(Williams syndrome, WS)患者的临床表型,并对文献复习,总结患者临床特征,以期提高临床医生对本病认识。方法:采集1例威廉姆斯综合征患者的临床资料,采集其静脉血应用全外显子测序,检索中英文数据库中已报道的威廉姆斯的相关病例,总结临床特征。结果:患儿具有前额宽、双颞窄、颧骨扁平以及短鼻伴长人中、厚唇、阔嘴的典型特殊面容,心脏彩超提示患儿患有主动脉瓣上狭窄,且患儿右侧上下肢的血压偏高,这与既往研究文献的特殊临床特征相吻合。经过全外显子测序和全基因组CNV的结果比对,确认7号染色体单杂合1.45Mb片段缺失为Del (7q11.23)。 梁洪柱, 鲍佳鹏, 张艳红 Adobe PDF Library 11.0 威廉姆斯综合征,基因检测,7q11.23区域 D:20250314061422 çł®çı—ï¼ıæ−¥å‚−1侉娆廛姃振综咋徆(Williams syndrome, WS)懣蕖çı—临åº−表垉$并对æŒ⁄焮夓乀$敻ç»fi懣蕖临åº−盹徆$以æœ�摒髟临åº−å„»çfl�å¯¹æœ¬çŠ–è®¤è¯ƒã•‡æŒ¹æ³Łï¼ıé⁄⁄éłƒ1侉娆廛姃振综咋徆懣蕖çı—临åº−赗挎$é⁄⁄éłƒå–¶éšŽè—›è¡•åºflçfl¨å–¨å¤ŒæŸ¾å�’浉庑$棕索ä¸�艱æŒ⁄æŁ°æ“®åºfiä¸�å·²æ−¥é†fiçı—娆廛姃振çı—çł¸å–³çŠ–ä¾‰ï¼„æ•»ç»fi临åº−盹徆㕇ç»fiæžœï¼ı懣嗿喷望囓颚宽㕆呄颞窗㕆颧骨曆平以å‘−ç��é¼»ä¼´éŁ¿äººä¸�㕆å”ıåfl⁄㕆éŸfl埴çı—喸垉盹æ®−隢容$必藑彩趖摒示懣嗿懣望主å−¨è—›çfi£ä¸−ç‰�窗$ä¸fl懣嗿味侧ä¸−三臢çı—衕唉冑髟$迎且抢徕ç€flç©¶æŒ⁄ç„®çı—盹æ®−临åº−ç›¹å¾†çł¸å’»å’‹ã•‡ç»‘è¿⁄喨夌柾å�’浉庑噄喨å�ºåł€ç»—CNVçı—ç»fiæžœæ¯fl对$确认7å‘·æ�fi蛲ä½fiå“Łæš‡å’‹1.45Mbç›⁄段缺失为Del (7q11.23)㕇 endstream endobj 27 0 obj <>stream h245U0Pw/+Q0L)64)I 14Q!vv?9 endstream endobj 28 0 obj <>stream hlRMLA 1B\B[gk$7qY5Poot@R',*fiav/GNqQ~-B${JTwݯ NC%4w"|QjIy|9KϚHc[~IBM -{_"_= mC l` endstream endobj 29 0 obj <>/Filter/FlateDecode/ID[<3748C384EEBEB64AADE5B4096F369D7E>]/Info 156 0 R/Length 154/Root 158 0 R/Size 157/Type/XRef/W[1 3 1]>>stream hbb&FVb& cG@$cX DkHfiO<Hec`})2pXlK,dHqՀM` 6y.Z iH?m om# b@!8  Y endstream endobj startxref 116 %%EOF